Tehran University of Medical Sciences Journal of Craniomaxillofacial Research 2345-5489 2026 2 2026 08 25 228 232 Bahareh Fattahi Department of Oral and Maxillofacial Pathology, School of Dentistry, Kashan University of Medical Sciences, Kashan, Iran. Arash Esmaeili Department of Oral and Maxillofacial Surgery, School of Dentistry, Isfahan University of Medical Sciences, Isfahan, Iran. Hasti Sarabi Kia Department of Oral and Maxillofacial Surgery, School of Dentistry, Isfahan University of Medical Sciences, Isfahan, Iran. 2026 05 12 2026 07 04 Maxillary osteoblastoma in children is exceptionally rare, accounting for fewer than 5% of all craniofacial cases. This benign bone tumor can closely mimic intraosseous hemangioma both clinically and radiographically due to its highly vascular stroma, leading to diagnostic pitfalls. We report a 5-year-old girl whose maxillary lesion exhibited soft, fluctuant swelling, reddish discoloration, bleeding on touch, and post-extraction hemorrhage—features strongly suggestive of hemangioma. A multidisciplinary approach involving maxillofacial surgery, radiology, and pathology was essential for definitive diagnosis. This case underscores that osteoblastoma must remain in the differential diagnosis of vascular-appearing pediatric maxillary masses, and multidisciplinary collaboration is critical to avoid misdiagnosis.  Keywords: Osteoblastoma; Maxilla; Hemangioma. https://jcr.tums.ac.ir/index.php/jcr/article/view/648 https://jcr.tums.ac.ir/index.php/jcr/article/download/648/501