Maxillary Osteoblastoma in a Child Mimicking Intraosseous Hemangioma: A Case Report
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Abstract
Maxillary osteoblastoma in children is exceptionally rare, accounting for fewer than 5% of all craniofacial cases. This benign bone tumor can closely mimic intraosseous hemangioma both clinically and radiographically due to its highly vascular stroma, leading to diagnostic pitfalls. We report a 5-year-old girl whose maxillary lesion exhibited soft, fluctuant swelling, reddish discoloration, bleeding on touch, and post-extraction hemorrhage—features strongly suggestive of hemangioma. A multidisciplinary approach involving maxillofacial surgery, radiology, and pathology was essential for definitive diagnosis. This case underscores that osteoblastoma must remain in the differential diagnosis of vascular-appearing pediatric maxillary masses, and multidisciplinary collaboration is critical to avoid misdiagnosis. Keywords: Osteoblastoma; Maxilla; Hemangioma.
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11. Giuffrida MA, Bacon NJ, Kamstock DA. Use of routine histopathology and factor VIII-related antigen/von Willebrand factor immunohistochemistry to differentiate primary hemangiosarcoma of bone from telangiectatic osteosarcoma. Vet Comp Oncol. 2017;15(4):1232-1239.
2. Gadwal SR, Gannon FH, Fanburg-Smith JC, Becoskie EM, Thompson LD. Primary osteosarcoma of the head and neck in pediatric patients: a clinicopathologic study of 22 cases with a review of the literature. Cancer. 2001;91(3):598-605.
3. Bertoni F, Unni KK, McLeod RA, Dahlin DC. Osteosarcoma of the jaws. Cancer. 1986;57(3):553-61.
4. Vella O, Cuny F, Robard L, Bazille C. Osteoblastoma of the maxillary sinus in a child presenting with exophthalmos. Eur Ann Otorhinolaryngol Head Neck Dis. 2016;133(4):277-279.
5. Bacot B, Eimer S, Berge J, De Gabory L. Osteoblastoma of the ethmoid sinus. Rev Laryngol Otol Rhinol (Bord). 2013;134(3):161-164.
6. Young E, Dabrowski M, Brelsford K. Osteoblastoma of the nasal septum. J Laryngol Otol. 2011;125(10):1062-1066.
7. Salmen FS, Oliveira MR, Navarro CM, Dedivitis RA, Pereira Filho VA, Gabrielli MFR. Aggressive Osteoblastoma in the Maxilla: Unusual Lesion in the Craniofacial Skeleton. J Craniofac Surg. 2017;28(3):794-797.
8. Badran KW, Suh JD, Namiri N, Wrobel B, Ference EH. Pediatric Benign Paranasal Sinus Osteoneogenic Tumors: A Case Series and Systematic Review of Outcomes, Techniques, and a Multiportal Approach. Am J Rhinol Allergy. 2018;32(6):465-472.
9. Mohammadi F, Derakhshan S, Shooshtarizadeh T, Sobhaninejad S. A rare case of maxillary osteoblastoma in a 10-month-old infant. Dent Res J (Isfahan). 2022; 19:13.
10. Kim Y, Lee J, Park S. Mandibular osteoblastoma: Report of 3 cases. J Korean Assoc Maxillofac Plast Reconstr Surg. 2010;32(2):168-172.
11. Giuffrida MA, Bacon NJ, Kamstock DA. Use of routine histopathology and factor VIII-related antigen/von Willebrand factor immunohistochemistry to differentiate primary hemangiosarcoma of bone from telangiectatic osteosarcoma. Vet Comp Oncol. 2017;15(4):1232-1239.
| Files | ||
| Issue | Vol 13, No 2 (Spring 2026) | |
| Section | Case Report(s) | |
| Keywords | ||
| Osteoblastoma; Maxilla; Hemangioma. | ||
| Rights and permissions | |
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This work is licensed under a Creative Commons Attribution-NonCommercial 4.0 International License. |
How to Cite
1.
Fattahi B, Esmaeili A, Sarabi Kia H. Maxillary Osteoblastoma in a Child Mimicking Intraosseous Hemangioma: A Case Report. J Craniomaxillofac Res. 2026;2026(2):228-232.
